A novel mutation in the NF1 gene in two siblings with neurofibromatosis type 1 and bilateral optic pathway glioma


Kebudi R., Tuncer S., Upadhyaya M., Peksayar G., Spurlock G., Yazici H.

PEDIATRIC BLOOD & CANCER, vol.50, no.3, pp.713-715, 2008 (SCI-Expanded, Scopus)

  • Publication Type: Article / Article
  • Volume: 50 Issue: 3
  • Publication Date: 2008
  • Doi Number: 10.1002/pbc.21234
  • Journal Name: PEDIATRIC BLOOD & CANCER
  • Journal Indexes: Science Citation Index Expanded (SCI-EXPANDED), Scopus
  • Page Numbers: pp.713-715
  • Keywords: gene mutation, neurofibromatosis type 1, Optic glioma, siblings, VONRECKLINGHAUSEN NEUROFIBROMATOSIS, TWINS
  • Istanbul University Affiliated: Yes

Abstract

We present the clinical and ophthalmological findings, genetic analysis, and therapy of two siblings with NF1 and bilateral OPG. In genetic analysis, a heteroduplex profile was detected in exon 4b of the NF1 gene for the affected patients and mother. Sequencing of the DNA samples identified a C > T nucleotide change in exon 4b (c484CAG > TAG). This nonsense mutation resulted in a change of glutamine to a stop codon (Q162X) and is a novel NF1 gene alteration.